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Journal : Malang Respiratory Journal

A Rare Case of Chylothorax Manifestation of Gorham’s Disease, Lymphangioma and Tuberculosis Agil Dananjaya; Setyawan, Ungky; Putra, Ngakan; Erawati, Dini; Isharanto, Artono; Norahmawati, Eviana; Irmansyah, Istan
Malang Respiratory Journal Vol. 4 No. 2 (2022): September 2022
Publisher : Universitaas Brawijaya

Show Abstract | Download Original | Original Source | Check in Google Scholar | DOI: 10.21776/ub.mrj.2022.004.02.1

Abstract

Background: Chylothorax is a rare condition caused by accumulation of chyle in the pleural cavity (2-3%). More rare causes are Gorham's disease and tuberculosis Case: A 31-year-old male complained of swelling left arm and shortness of breath with recurrent pleural effusion. Pleural fluid analysis showed chylous. Bone survey showed osteolytic lesions of multiple bones as Gorham's disease. Thoracic CT showed left lung mass, atelectasis, massive fluidothorax, ipsilateral supraclavicular lymphadenopathy, destructive left scapula. Needleaspiration of left humerus revealed lymphangioma. Expert Mtb-Rif examination revealed Mtb detected. We assessed Gorham'sdisease, lymphangioma and lung tuberculosis with complication recurrent chylothorax and was treated anti-tuberculosis, anti-osteolytic and thorax catheter insertion. Conclusion: Difficult and rare case of chylothorax in one patient with Gorham’s disease and tuberculosis, is a poor prognosis. Keywords: Chylothorax, Gorham's Disease, Tuberculosis
Co-Authors A.A. Ketut Agung Cahyawan W Adilah Ulfiati Adilah Ulfiati, Adilah Agil Dananjaya Aina Angelina Ainun Ganisia Aliesya Patricia Amalia Pradanti Widarso, Amalia Pradanti Ardhian Wardana Ardhian Wardana, Ardhian Aris Rosidah Dian Sutarini, Ni Luh Gede Didiek Darmadi Ts Dwi Yuni Nur Hidayati Ega Prosfera, Rahma Haryunita Elisa Danik Kurniawati Endah Wijayanti Erawati, Dini Ervina, Rita Fadli, Muhammad Luqman Fitriana Nugraheni Fitriana Nugraheni, Fitriana Frenty Hadiningsih, Eka Hamka Muhammad Nasir Laitupa Harun Al Rasyid Harun Al Rasyid Herpan Syafii Harahap Ihda Dian Kusuma Ineke Permatasari Irmansyah, Istan Irsan, Istan Irmansyah Isharanto, Artono Kenty Wantri Anita, Kenty Wantri Kurnia Penta Seputra Laitupa, Hamka Muhammad Nasir Loeki Enggar Fitri lumban gaol, andy MIFTAHUL JANNAH Miftahul Jannah Mochammad Dalhar Nabila, Astrid Hanan Nanik Setijowati Ni Putu Sri Haryati Noorhamdani Nur Fahma Pradiptasari Nur Fahma Pradiptasari, Nur Fahma Nurdiana Nurdiana Pratista Adi Krisna, Pratista Adi Pratiwi, Suryanti Dwi Putra, Ngakan Putra, Ngakan Putu Putri Ardela, Mayasari RA Rose Khasana Dewi Rachmad Sarwo Bekti Rahmana, Rahima Azzahra Retnani, Diah Prabawati Retty Ratnawati Ririn Handayani Rose Dewi Sawitri, Lia Setyawan, Ungky Sri Winarsih Sujarot Dwi Sasmito sujarot dwi sasmito, sujarot dwi SURYANTI Tanti Tri Lestary Tatit Nurseta Teguh Prihanto Teguh Wahju Sardjono Teguh Wahju Sardjono Tinny Endang Endang H Ulfaningtyas, Kiki Wati, Linda Ratna Wiyasa, I Wayan Arsana Yahya Irwanto Yudhanto, Hendy Setyo Zakiyah Zulaifa Zakiyah Zulaifa, Zakiyah